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Mevalonic aciduria. Mevalonate kinase deficiency

Incidence

Very rare. Eleven cases reported up to 1993. Two forms: early and late (6-12 months) infantile forms. It is a branched chain organic aciduria. Disorder of cholesterol biosynthesis. No patients reported in Saudi Arabia.

Clinical Characteristics

Triangular face,down-slanted eyes, large posteriorly rotated low-set ears, cataracts, seizures. FTT, hepatosplenomegaly, thrombocytopenia, anemia, leucocytosis, severe gastroenteritis, early generalized brain atrophy. Hypotonia & high CPK in late infantil

Precipitants

none

Provocation Tests

no

Diagnostic Procedures

Mevalonate kinase deficiency: EB-F, W, and liver. Blood cholesterol 70-80 mg%.

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